Comprehensive treatment of non-syndromic multiple odontogenic keratocyst and impacted teeth in a pediatric patient—a case report and literature review

Background: The odontogenic keratocyst (OKC) is a developmental cyst that is considered benign but displays localized aggressiveness. Most patients with multiple OKCs present with syndromes, and non-syndromic patients with multiple OKCs are less common. Furthermore, there is a lack of information on the management of non-systemic multiple OKCs and the associated problems. Further investigation is needed to explore the efficacy of comprehensive treatment for OKC patients with large cysts and impacted teeth. Case: In this case, we presented a case of a 10-year-old patient with non-syndromic multiple OKCs and impacted teeth. A panoramic radiograph revealed two radiolucent areas in the mandible. To remove the lesions and promote the eruption of impacted teeth, a comprehensive therapy involving marsupialization, enucleation, obturator and orthodontic alignment was employed. Asymmetry of the mandible, alveolar bone and occlusal plane, in addition to the presence of a deep overbite, were observed during the course of treatment. Conclusions: This case underscores the effectiveness of comprehensive OKC treatment and highlights the potential impact of cysts and impacted teeth on jaw and dentition symmetry.

Odontogenic keratocyst; Keratocystic odontogenic tumor; Impacted tooth; Marsupialization; Orthodontic treatment

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